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Intraosseous leiomyoma of the distal femur: a case report and review of literatures

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Abstract

Background

Leiomyoma is a benign tumor of smooth-muscle origin. They most commonly derived from the uterus. Besides, they were also usually diagnosed in the gastrointestinal tract, skin, and mucous membranes. However, it rarely occurs in the bone.

Case presentation

The authors reported one case of 56-year-old male with intraosseous leiomyoma of the distal femur. Initially, the patient felt left knee pain for 1 year. Radiographs film disclosed an ill-defined osteolytic lesion with thinning cortex over left distal femoral medial condylar region. Computed tomography (CT) revealed homogenous radiolucent lesion with thinning cortex over the metaphysis of distal femur. Magnetic resonance imaging showed focal marrow replacement by tumor. CT-guide biopsy was performed, and the pathology showed a picture of leiomyoma. Since the definite diagnosis, the lesion was treated with en-bloc resection and endoprosthetic knee joint reconstruction. Satisfied result and disease free were achieved during follow-up.

Conclusions

Intraosseous leiomyoma of the extremities is difficult to be diagnosed due to extraordinarily rare. This rare benign tumor should be included in the differential diagnosis of any relatively intraosseous lesion with benign imaging findings. This is the first published case of primary intraosseous leiomyoma of distal femur after literature reviews.

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Acknowledgments

The report was not supported by any foundation. However, we deeply appreciate Dr. Keun-Huang Chen and Dr. Meng-Yuan Tsai for their expert reading of radiological image.

Conflict of interest

The authors declare that there are no conflicts of interest.

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Authors and Affiliations

  1. Department of Orthopedics, Kaohsiung Veterans General Hospital, 386 Ta-Chung 1st Road, Kaohsiung City, Taiwan

    Yu-Hsiang Sung, Shan-Wei Yang, Yih-Wen Tarng & Chien-Jen Hsu

  2. Department of Biomedical Engineering, I-Shou University, Kaohsiung County, Taiwan

    Shan-Wei Yang & Shwu-Jen Chang

  3. Department of Electrical Engineering, I-Shou University, Kaohsiung County, Taiwan

    Shan-Wei Yang & Lain-Chyr Hwang

Authors
  1. Yu-Hsiang Sung
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  2. Shan-Wei Yang
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  3. Yih-Wen Tarng
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  4. Shwu-Jen Chang
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  5. Chien-Jen Hsu
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Corresponding author

Correspondence to Shan-Wei Yang.

Additional information

Yu-Hsiang Sung and Shan-Wei Yang contributed equally to this work.

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Sung, YH., Yang, SW., Tarng, YW. et al. Intraosseous leiomyoma of the distal femur: a case report and review of literatures. Eur J Orthop Surg Traumatol 22 (Suppl 1), 161–165 (2012). https://doi.org/10.1007/s00590-011-0874-y

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  • DOI: https://doi.org/10.1007/s00590-011-0874-y

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