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Posterior median surgical approach to anterior sacral meningocele complicated by rectothecal fistula

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Abstract

In this case report, we aimed to describe the clinical presentation, surgical approach, and follow-up of a patient with rare anterior meningocele associated with rectothecal fistula. An 17-year-old female patient was admitted to the emergency department with meningitis. On further examinations, an anterior sacral meningocele accompanied by rectothecal fistula was detected. Appropriate antibiotic treatment was arranged and surgical plan was made with the pediatric surgery clinic. The patient underwent meningocele repair via posterior approach and colostomy operation. The patient did not experience any neurological issues after the surgery. The colostomy was reversed 3 months later, and third-month follow-up MRI showed complete regression of the meningocele sac with no neurological complications. Anterior meningocele accompanied by a rectothecal fistula is a rare and complicated case. Only seven cases of coexisting ASM and RTF have been reported in literature. Although both anterior and posterior approaches have been used for the treatment of ASM, the choice of treatment is essentially based on the patient’s clinical and imaging findings.

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Abbreviations

ASM:

Anterior sacral meningocele

CSF:

Cerebrospinal fluid

DoA:

Day of admission

LP:

Lumbar puncture

MRI:

Magnetic resonance imaging

POD:

Postoperative day

RTF:

Rectothecal fistula

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E.E., E.B., and M.T. wrote the main manuscript text. E.E. prepared figures. O.O., E.B., E.ERG.: surgical planning, informing patient and relatives, obtaining consent. All authors reviewed the manuscript.

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Correspondence to Onur Ozgural.

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Erdin, E., Bayatli, E., Terzi, M. et al. Posterior median surgical approach to anterior sacral meningocele complicated by rectothecal fistula. Childs Nerv Syst 40, 1295–1299 (2024). https://doi.org/10.1007/s00381-024-06286-y

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  • DOI: https://doi.org/10.1007/s00381-024-06286-y

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