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A rare and unexpected clinical progress and location on a primary extradural spinal hydatid cyst in a pediatric patient: a case report

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Abstract

Background

Involvement of spine in patients with hydatid disease (HD) is less than 1 % and primary intra-spinal extradural HD is extremely rare. Although this disease is introduced as benign pathology according to its clinical presentation and biological behavior, intraoperative rupture of the cyst may aggravate the patients’ outcome in the long-term especially in pediatric patient population.

Case presentation

We report a 9-year-old girl who presented a progressive neurological deterioration due to an enlargement of a ventrally located extradural hydatid cyst within the thoracic spinal canal. Total removal of the cyst was achieved by preserving the capsule integrity for preventing potential seeding. Our preoperative initial diagnosis based on the radiological findings was confirmed as cyst hydatid histopathologically.

Conclusion

Cyst hydatid should be considered in the differential diagnosis of the presence of homogenous cystic lesions with regular shape inside the spinal canal especially in patients from endemic region. To our knowledge, this pediatric patient is the first case of cyst hydatid located ventral side of the spinal cord extradurally located inside the spinal canal showing no extension.

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Conflict of interest

All authors have no conflict of interest.

Informed consent

Informed consent of the case is obtained from the parents of the patient.

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Authors and Affiliations

  1. Department of Neurosurgery, School of Medicine, Ankara University, Sihhiye, 06100, Ankara, Turkey

    Ihsan Dogan, Gokmen Kahilogullari, Efe Guner & Agahan Unlu

Authors
  1. Ihsan Dogan
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  2. Gokmen Kahilogullari
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  3. Efe Guner
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  4. Agahan Unlu
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Corresponding author

Correspondence to Gokmen Kahilogullari.

Additional information

This article was introduced as a poster presentation in the 24th ESPN Congress, Rome.

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Dogan, I., Kahilogullari, G., Guner, E. et al. A rare and unexpected clinical progress and location on a primary extradural spinal hydatid cyst in a pediatric patient: a case report. Childs Nerv Syst 31, 1407–1411 (2015). https://doi.org/10.1007/s00381-015-2728-0

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  • DOI: https://doi.org/10.1007/s00381-015-2728-0

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